ZFIN All Figures, Serafini <i>et al.</i>, 2018

Fig. 1

ZFIN is incorporating published figure images and captions as part of an ongoing project. Figures from some publications have not yet been curated, or are not available for display because of copyright restrictions.

PHENOTYPE:

Fish:	fkrp^{uab203/uab203} (AB) fkrp^{uab204/uab204} (AB) fkrp^{uab205/uab205} (AB)
Observed In:	pericardium
Stage:	Day 5

Phenotype details

Fig. 2

ZFIN is incorporating published figure images and captions as part of an ongoing project. Figures from some publications have not yet been curated, or are not available for display because of copyright restrictions.

PHENOTYPE:

Fish:	dmd^{ta222a/ta222a} fkrp^{uab203/uab203} (AB)
Observed In:	locomotory behavior thigmotaxis
Stage:	Day 5

Phenotype details

Fig. 3

ZFIN is incorporating published figure images and captions as part of an ongoing project. Figures from some publications have not yet been curated, or are not available for display because of copyright restrictions.

EXPRESSION / LABELING:

Genes:	atf4a atf4b atf6 atf6b eif2ak3 ern1 hspa5 xbp1
Fish:	AB fkrp^{uab203/uab203} (AB)
Anatomical Term:	whole organism
Stage:	Day 5

Expression / Labeling details

PHENOTYPE:

Fish:	fkrp^{uab203/uab203} (AB)
Observed In:	whole organism
Stage:	Day 5

Phenotype details

Fig. 4

ZFIN is incorporating published figure images and captions as part of an ongoing project. Figures from some publications have not yet been curated, or are not available for display because of copyright restrictions.

PHENOTYPE:

Fish:	fkrp^{uab203/uab203}; uab202Tg
Condition:	heat shock
Observed In:	post-vent region skeletal muscle cell
Stage:	Day 5

Phenotype details

Fig. 5

ZFIN is incorporating published figure images and captions as part of an ongoing project. Figures from some publications have not yet been curated, or are not available for display because of copyright restrictions.

PHENOTYPE:

Fish:	fkrp^{uab203/uab203}; uab202Tg
Conditions:	heat shock chemical treatment: pentetic acid, heat shock
Observed In:	pericardium skeletal muscle whole organism
Stage Range:	Day 5 to Days 7-13

Phenotype details

Fig. 6

ZFIN is incorporating published figure images and captions as part of an ongoing project. Figures from some publications have not yet been curated, or are not available for display because of copyright restrictions.

PHENOTYPE:

Fish:	fkrp^{uab203/uab203}; uab202Tg
Conditions:	chemical treatment: citric acid, heat shock chemical treatment: pentetic acid, heat shock chemical treatment: triethanolamine, heat shock
Observed In:	pericardium skeletal muscle
Stage:	Day 5

Phenotype details

Fig. S2

ZFIN is incorporating published figure images and captions as part of an ongoing project. Figures from some publications have not yet been curated, or are not available for display because of copyright restrictions.

EXPRESSION / LABELING:

Genes:	b4gat1 crppa dag1 fkrp fktn large1 pomgnt1 pomgnt2 pomk pomt1
Fish:	AB fkrp^{uab203/uab203} (AB)
Anatomical Term:	whole organism
Stage:	Day 5

Expression / Labeling details

PHENOTYPE:

Fish:	fkrp^{uab203/uab203} (AB)
Observed In:	whole organism
Stage:	Day 5

Phenotype details

Table 1

ZFIN is incorporating published figure images and captions as part of an ongoing project. Figures from some publications have not yet been curated, or are not available for display because of copyright restrictions.

PHENOTYPE:

Fish:	fkrp^{uab203/uab203}; uab202Tg
Conditions:	chemical treatment: alverine citrate, heat shock chemical treatment: aztreonam, heat shock chemical treatment: betulin, heat shock chemical treatment: calycanthine, heat shock chemical treatment: chlorphenesin carbamate, heat shock chemical treatment: streptomycins, heat shock chemical treatment: flumequine, heat shock chemical treatment: ipratropium bromide, heat shock chemical treatment: Kawain, heat shock chemical treatment: metampicillin sodium, heat shock chemical treatment: metaraminol bitartrate, heat shock chemical treatment: ornidazole, heat shock chemical treatment: oxymetazoline hydrochloride, heat shock chemical treatment: paclitaxel, heat shock chemical treatment: perphenazine, heat shock chemical treatment: pirenzepine hydrochloride, heat shock chemical treatment: rimexolone, heat shock chemical treatment: sulfacetamide sodium, heat shock chemical treatment: Thioproperazine mesilate, heat shock chemical treatment: ursolic acid, heat shock
Observed In:	eye head pericardium skeletal muscle whole organism
Stage:	Day 5

Phenotype details

text only

Unillustrated author statements

PHENOTYPE:

Fish:	fkrp^{uab203/uab203} (AB)
Observed In:	brain eye muscle whole organism
Stage Range:	Day 5 to Days 7-13

Phenotype details

Acknowledgments

Full text @ JCI Insight

Serafini et al., 2018

ZDB-PUB-180921-12
PMID:30232282

A limb-girdle muscular dystrophy 2I model of muscular dystrophy identifies corrective drug compounds for dystroglycanopathies

Serafini et al., 2018 ZDB-PUB-180921-12 PMID:30232282

A limb-girdle muscular dystrophy 2I model of muscular dystrophy identifies corrective drug compounds for dystroglycanopathies

Serafini et al., 2018

ZDB-PUB-180921-12
PMID:30232282