PUBLICATION

Phosphorylation of H3-Thr3 by Haspin Is Required for Primary Cilia Regulation

Authors
Quadri, R., Sertic, S., Ghilardi, A., Rondelli, D., Gallo, G.R., Del Giacco, L., Muzi-Falconi, M.
ID
ZDB-PUB-210728-9
Date
2021
Source
International Journal of Molecular Sciences   22(14): (Journal)
Registered Authors
Del Giacco, Luca, Ghilardi, Anna
Keywords
Dido3, H3T3, HDAC6, Haspin, ciliopathy, primary cilia, zebrafish
MeSH Terms
  • Animals
  • Cell Cycle/physiology
  • Cells, Cultured
  • Chromatin/metabolism
  • Cilia/metabolism*
  • HEK293 Cells
  • Histones/metabolism*
  • Humans
  • Intracellular Signaling Peptides and Proteins/metabolism*
  • Phosphorylation/physiology*
  • Protein Serine-Threonine Kinases/metabolism*
  • Threonine/metabolism*
  • Zebrafish
PubMed
34299370 Full text @ Int. J. Mol. Sci.
Abstract
Primary cilia are commonly found on most quiescent, terminally differentiated cells and play a major role in the regulation of the cell cycle, cell motility, sensing, and cell-cell communication. Alterations in ciliogenesis and cilia maintenance are causative of several human diseases, collectively known as ciliopathies. A key determinant of primary cilia is the histone deacetylase HDAC6, which regulates their length and resorption and whose distribution is regulated by the death inducer-obliterator 3 (Dido3). Here, we report that the atypical protein kinase Haspin is a key regulator of cilia dynamics. Cells defective in Haspin activity exhibit longer primary cilia and a strong delay in cilia resorption upon cell cycle reentry. We show that Haspin is active in quiescent cells, where it phosphorylates threonine 3 of histone H3, a known mitotic Haspin substrate. Forcing Dido3 detachment from the chromatin prevents Haspin inhibition from impacting cilia dynamics, suggesting that Haspin activity is required for the relocalization of Dido3-HDAC6 to the basal body. Exploiting the zebrafish model, we confirmed the physiological relevance of this mechanism. Our observations shed light on a novel player, Haspin, in the mechanisms that govern the determination of cilia length and the homeostasis of mature cilia.
Genes / Markers
Figures
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Expression
Phenotype
Mutations / Transgenics
Human Disease / Model
Sequence Targeting Reagents
Fish
Antibodies
Orthology
Engineered Foreign Genes
Mapping