PUBLICATION

Divergent roles of the Wnt/PCP Formin Daam1 in renal ciliogenesis

Authors
Corkins, M.E., Krneta-Stankic, V., Kloc, M., McCrea, P.D., Gladden, A.B., Miller, R.K.
ID
ZDB-PUB-190902-13
Date
2019
Source
PLoS One   14: e0221698 (Journal)
Registered Authors
Miller, Rachel K
Keywords
none
MeSH Terms
  • Adaptor Proteins, Signal Transducing/genetics*
  • Adaptor Proteins, Signal Transducing/metabolism*
  • Animals
  • Cell Differentiation/genetics*
  • Cells, Cultured
  • Cilia/metabolism*
  • Ciliopathies/etiology
  • Ciliopathies/metabolism
  • Ciliopathies/pathology
  • Epithelial Cells/metabolism*
  • Formins
  • Gene Knockdown Techniques
  • Kidney/cytology*
  • Phenotype
  • Wnt Proteins/metabolism*
  • Wnt Signaling Pathway
  • Xenopus Proteins/genetics*
  • Xenopus Proteins/metabolism*
  • Xenopus laevis
PubMed
31469868 Full text @ PLoS One
Abstract
Kidneys are composed of numerous ciliated epithelial tubules called nephrons. Each nephron functions to reabsorb nutrients and concentrate waste products into urine. Defects in primary cilia are associated with abnormal formation of nephrons and cyst formation in a wide range of kidney disorders. Previous work in Xenopus laevis and zebrafish embryos established that loss of components that make up the Wnt/PCP pathway, Daam1 and ArhGEF19 (wGEF) perturb kidney tubulogenesis. Dishevelled, which activates both the canonical and non-canonical Wnt/PCP pathway, affect cilia formation in multiciliated cells. In this study, we investigated the role of the noncanoncial Wnt/PCP components Daam1 and ArhGEF19 (wGEF) in renal ciliogenesis utilizing polarized mammalian kidney epithelia cells (MDCKII and IMCD3) and Xenopus laevis embryonic kidney. We demonstrate that knockdown of Daam1 and ArhGEF19 in MDCKII and IMCD3 cells leads to loss of cilia, and Daam1's effect on ciliogenesis is mediated by the formin-activity of Daam1. Moreover, Daam1 co-localizes with the ciliary transport protein Ift88 and is present in cilia. Interestingly, knocking down Daam1 in Xenopus kidney does not lead to loss of cilia. These data suggests a new role for Daam1 in the formation of primary cilia.
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