PUBLICATION

Carbonic anhydrase 5 regulates Acid-base homeostasis in zebrafish

Authors
Postel, R., and Sonnenberg, A.
ID
ZDB-PUB-120706-2
Date
2012
Source
PLoS One   7(6): e39881 (Journal)
Registered Authors
Postel, Ruben
Keywords
none
MeSH Terms
  • Acid-Base Equilibrium/genetics
  • Acid-Base Equilibrium/physiology
  • Animals
  • Carbonic Anhydrase V/genetics
  • Carbonic Anhydrase V/metabolism*
  • Embryonic Development
  • Homeostasis/genetics
  • Homeostasis/physiology
  • Hydrogen-Ion Concentration
  • Zebrafish
  • Zebrafish Proteins/genetics
  • Zebrafish Proteins/metabolism*
PubMed
22745834 Full text @ PLoS One
Abstract

The regulation of the acid-base balance in cells is essential for proper cellular homeostasis. Disturbed acid-base balance directly affects cellular physiology, which often results in various pathological conditions. In every living organism, the protein family of carbonic anhydrases regulate a broad variety of homeostatic processes. Here we describe the identification, mapping and cloning of a zebrafish carbonic anhydrase 5 (ca5) mutation, collapse of fins (cof), which causes initially a collapse of the medial fins followed by necrosis and rapid degeneration of the embryo. These phenotypical characteristics can be mimicked in wild-type embryos by acetazolamide treatment, suggesting that CA5 activity in zebrafish is essential for a proper development. In addition we show that CA5 regulates acid-base balance during embryonic development, since lowering the pH can compensate for the loss of CA5 activity. Identification of selective modulators of CA5 activity could have a major impact on the development of new therapeutics involved in the treatment of a variety of disorders.

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Mapping