PUBLICATION

CSAP localizes to polyglutamylated microtubules and promotes proper cilia function and zebrafish development

Authors
Backer, C.B., Gutzman, J.H., Pearson, C.G., and Cheeseman, I.M.
ID
ZDB-PUB-120412-14
Date
2012
Source
Molecular biology of the cell   23(11): 2122-2130 (Journal)
Registered Authors
Gutzman, Jennifer
Keywords
none
MeSH Terms
  • Animals
  • Body Patterning/genetics
  • Brain/embryology
  • Brain/metabolism
  • Centrioles/metabolism
  • Cilia/metabolism*
  • Embryo, Nonmammalian/metabolism
  • Gene Expression Regulation, Developmental
  • HeLa Cells
  • Humans
  • Microtubule-Associated Proteins/metabolism*
  • Microtubules/metabolism*
  • Neurons/cytology
  • Neurons/metabolism
  • Polyglutamic Acid/metabolism*
  • Protein Transport
  • Spindle Apparatus/metabolism
  • Zebrafish/embryology*
  • Zebrafish/genetics
  • Zebrafish/metabolism*
  • Zebrafish Proteins/metabolism*
PubMed
22493317 Full text @ Mol. Biol. Cell
Abstract

The diverse populations of microtubule polymers in cells are functionally distinguished by different posttranslational modifications including polyglutamylation. Polyglutamylation is enriched on subsets of microtubules including those found in the centrioles, mitotic spindle, and cilia. However, whether this modification alters intrinsic microtubule dynamics or affects extrinsic associations with specific interacting partners remains to be determined. Here, we identify the microtubule binding protein Centriole and Spindle Associated Protein (CSAP), which colocalizes with polyglutamylated tubulin to centrioles, spindle microtubules, and cilia in human tissue culture cells. Reducing tubulin polyglutamylation prevents CSAP localization to both spindle and cilia microtubules. In zebrafish, CSAP is required for normal brain development and proper left-right asymmetry, defects qualitatively similar to those reported previously for depletion of polyglutamylation conjugating enzymes. We also find that CSAP is required for proper cilia beating. Our work supports a model in which polyglutamylation can target selected microtubule-associated proteins, such as CSAP, to microtubule subpopulations providing specific functional capabilities to these populations.

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